Clinical and genetic landscape of IGHMBP2 -related disorders: From novel variants to phenotypic insights

Document Type

Case Report

Department

Paediatrics and Child Health; Neurology

Abstract

Pathogenic variants in IGHMBP2 have been associated with spinal muscular atrophy with respiratory distress type 1 (SMARD1) and Autosomal Recessive Charcot-Marie-Tooth disease type 2S (AR-CMT2S), as well as a relatively wide spectrum of rare, atypical phenotypes. We describe clinical and molecular features of five patients who have diverse clinical findings associated with known and novel IGHMBP2 pathogenic variants. Genotype-phenotype correlations are evident, highlighting the association of specific variants with SMARD1 or AR-CMT2S. This study expands the spectrum of the IGHMBP2-related disease and highlights the necessity to study diverse populations to enhance diagnostic accuracy and refine genotype-phenotype correlations.

Comments

Pagination are not provided by the author/publisher.

Publication (Name of Journal)

American Journal of Medical Genetics. Part A

DOI

10.1002/ajmg.a.64116

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